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Zanubrutinib in Patients With IgG4-Related Disease

Phase 2
Completed
Conditions
IgG4 Related Disease
Interventions
Registration Number
NCT04602598
Lead Sponsor
Matthew C. Baker
Brief Summary

The aim of this clinical trial is to evaluate the safety and efficacy of zanubrutinib in treating patients with IgG4-related disease

Detailed Description

This will be a single-site, open-label study in symptomatic patients with IgG4-related disease affecting the submandibular and/or lacrimal glands. All patients will receive zanubrutinib orally at a dose of 80mg BID for 24 weeks.

The primary objective of this study is to demonstrate that zanubrutinib treatment reduces reduces the volume of the submandibular and/or lacrimal glands on PET/MRI at week 24 compared to baseline.

Recruitment & Eligibility

Status
COMPLETED
Sex
All
Target Recruitment
10
Inclusion Criteria
  • Men or women aged 18 to 85, inclusive, at the time of initial screening

  • Have histopathologically confirmed IgG4-RD in the submandibular gland and/or the lacrimal gland confirmed by international consensus pathology criteria

    • Presence of a lymphoplasmacytic infiltrate with 10 IgG4+ plasma cells per high-power field and/or an IgG4+/IgG+ plasma cell ratio of 40%
  • All women must test negative for pregnancy and agree to use a reliable method of birth control

  • No current treatment with immunosuppressive medications other than prednisone 40mg daily (or other glucocorticoid equivalent) with stable dosing for 28 days

Exclusion Criteria
  • Unstable prescribed dose of glucocorticoids within 28 days prior to baseline
  • Any treatment with a synthetic DMARD including but not limited to hydroxychloroquine, methotrexate, leflunomide, or sulfasalazine within 28 days prior to baseline
  • Any treatment with a cytotoxic or immunosuppressive drug including but not limited to cyclophosphamide, mycophenolic acid, azathioprine, cyclosporine, sirolimus, or tacrolimus within 28 days prior to baseline
  • Any treatment with a BTK inhibitor within 6 months before baseline
  • Any treatment with a JAK inhibitor within 28 days prior to baseline
  • Use of biologic agents including infliximab, abatacept, or tocilizumab within 56 days prior to baseline
  • Use of a B cell depleting therapy (such as rituximab) within 12 months prior to baseline
  • A history of, or current, inflammatory or autoimmune disease (that could affect the interpretation of safety or efficacy outcomes) other than IgG4-related disease
  • Evidence of active tuberculosis, HIV, or hepatitis B or C infection
  • History of cancer other than non-melanoma skin cancer, cervical dysplasia or carcinoma in situ (cured >1 year), prostate cancer (cured >5 years), or colon cancer (cured >5 years)

Study & Design

Study Type
INTERVENTIONAL
Study Design
SINGLE_GROUP
Arm && Interventions
GroupInterventionDescription
ZanubrutinibZanubrutinib 80 MGZanubrutinib orally at a dose of 80mg BID for 24 weeks
Primary Outcome Measures
NameTimeMethod
Volume of the lacrimal glands on PET-MRIBaseline to Week 24

To demonstrate that zanubrutinib treatment reduces the volume of the lacrimal glands on PET-MRI at Week 24 compared to Baseline.

Volume of the submandibular glands on PET-MRIBaseline to Week 24

To demonstrate that zanubrutinib treatment reduces the volume of the submandibular glands on PET-MRI at Week 24 compared to Baseline.

Secondary Outcome Measures
NameTimeMethod
FDG avidity (SUVmax) of the submandibular glands on PETBaseline to Week 24

Effect of zanubrutinib on change in FDG avidity (SUVmax) of the submandibular glands on PET at Week 24 compared to Baseline.

FDG avidity (SUVmax) of the lacrimal glands on PETBaseline to Week 24

Effect of zanubrutinib on change in FDG avidity (SUVmax) of the lacrimal glands on PET at Week 24 compared to Baseline.

Change in metabolic lesion volume (MLV) of submandibular and/or lacrimal glands on PETBaseline to Week 12
Change in total lesion glycolysis (TLG) of submandibular and/or lacrimal glands on PETBaseline to Week 12
Change in submandibular glands on MRIBaseline to Week 12

Change in parenchymal architecture scored 0 to 4 and sialography scored 0 to 4

Change in parotid glands on MRIBaseline to Week 12

Change in parenchymal architecture scored 0 to 4 and sialography scored 0 to 4

Change in lacrimal glands on MRIBaseline to Week 12

Change in parenchmyal architecture scored 0 to 4 and sialography scored 0 to 4

Change in the volume of the parotid glands on PET/MRIBaseline to Week 12
Change in the volume of the submandibular glands on PET/MRIBaseline to Week 12
Change in the volume of the lacrimal glands on PET/MRIBaseline to Week 12
FDG avidity (SUVmax) of the submandibular and/or lacrimal glands on PETBaseline to Week 12

Effect of zanubrutinib on change in FDG avidity (SUVmax) of the submandibular and/or lacrimal glands on PET at Week 12 compared to Baseline.

Change in serum IgG4 levelBaseline to Week 12
Change in plasmablast countBaseline to Week 12
Change in absolute regulatory B cell countBaseline to Week 12
Change in the IgG4-RD Responder IndexBaseline to Week 12
Proportion of patients with no disease flaresWeek 12 to Week 24
Change in total salivary grey scale ultrasound score (TUS)Baseline to Week 12

Each parotid and submandibular gland scored from 0 to 3 with a higher score indicating worse disease, total summed scores across all four glands will be assessed for change

Change in highest score among the salivary glands for the grey scale ultrasound score (HSUS)Baseline to Week 12

Each parotid and submandibular gland scored from 0 to 3 with a higher score indicating worse disease, highest score will be assessed for change

Change in glandular inflammation total ultrasound score (iTUS)Baseline to Week 12

Each parotid and submandibular gland scored from 0 to 3 with a higher score indicating worse disease, total summed scores across all four glands will be assessed for change

Change in highest score among the salivary glands for the glandular inflammation ultrasound score (iHSUS)Baseline to Week 12

Each parotid and submandibular gland scored from 0 to 3 with a higher score indicating worse disease, highest score will be assessed for change

Change in physician global assessment of diseaseBaseline to Week 12

Symptoms rated on a 100 mm VAS. Score range: 0 to 100, higher scores correspond to worse disease state.

Change in patient global assessment of diseaseBaseline to Week 12

Symptoms rated on a 100 mm VAS. Score range: 0 to 100, higher scores correspond to worse disease state.

Change in VAS for ocular symptomsBaseline to Week 12

Symptoms rated on a 100 mm VAS. Score range: 0 to 100, higher scores correspond to worse disease state.

Change in VAS for salivary symptomsBaseline to Week 12

Symptoms rated on a 100 mm VAS. Score range: 0 to 100, higher scores correspond to worse disease state.

Change in FACIT-F fatigue scoreBaseline to Week 12

Total score range: 0-52, lower scores correspond with more fatigue.

Change in RAND Short Form-36Baseline to Week 12
Change in C3 labBaseline to Week 12
Change in C4 labBaseline to Week 12
Change in total IgG labBaseline to Week 12
Change in IgE labBaseline to Week 12
Change in IgG1 labBaseline to Week 12
Change in ESR labBaseline to Week 12
Change in CRP labBaseline to Week 12
Incidence of safety parameters including adverse eventsBaseline to Week 32
Incidence of safety parameters including abnormal laboratory resultsBaseline to Week 32

Trial Locations

Locations (1)

Stanford University

🇺🇸

Palo Alto, California, United States

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