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Endogenous Glucose Production in Subjects with Glycogen Storage Disease Type Ia estimated by a single oral dose of stable isotopes: an investigator-initiated human pilot study.

Completed
Conditions
Glycogen Storage Disease Type Ia (GSDIa) & Von Gierke's Disease
10021605
Registration Number
NL-OMON50039
Lead Sponsor
niversitair Medisch Centrum Groningen
Brief Summary

Not available

Detailed Description

Not available

Recruitment & Eligibility

Status
Completed
Sex
Not specified
Target Recruitment
20
Inclusion Criteria

In order to be eligible to participate in this study, The GSDIa patients must
meet all of the following criteria:
• The diagnosis should be confirmed by G6PC mutation analysis
• Age above 16 years
• Stable medical condition before the start of the test procedures

Exclusion Criteria

A potential GSD Ia patient who meets any of the following criteria will be
excluded from participation in this study:
• Age < 16 years
• Recent (< 1 month) history of hospitalization due to hypoglycaemia
• Intercurrent illness, defined as (a combination of) decreased dietary intake,
vomiting, diarrhoea and fever (>38.5*C) in the week prior to the visit
• Pregnancy

A potential age and gender-matched healthy participant who meets any of the
following criteria will be excluded from participation in this study:
• Confirmed diagnosis or history suggestive of diabetes mellitus
• First grade family member with a confirmed diagnosis associated with fasting
intolerance
• History suggestive of fasting intolerance

Study & Design

Study Type
Observational invasive
Study Design
Not specified
Primary Outcome Measures
NameTimeMethod
<p>The main study parameter is the EGP quantification assessed by measurement of<br /><br>blood D-[6,6-2H2]glucose enrichment. </p><br>
Secondary Outcome Measures
NameTimeMethod
<p>Secondary study parameters are glucose area under the curve, glucose clearance<br /><br>rate, glucose bioavailability, glucose apparent volume of distribution and CGM<br /><br>data. </p><br>
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