MedPath

ONC201 in H3 K27M-mutant Diffuse Glioma Following Radiotherapy (the ACTION Study)

Phase 3
Recruiting
Conditions
H3 K27M
Glioma
Interventions
Registration Number
NCT05580562
Lead Sponsor
Chimerix
Brief Summary

This is a randomized, double-blind, placebo-controlled, parallel-group, international, Phase 3 study in patients with newly diagnosed H3 K27M-mutant diffuse glioma to assess whether treatment with ONC201 following frontline radiotherapy will extend overall survival and progression-free survival in this population. Eligible participants will have histologically diagnosed H3 K27M-mutant diffuse glioma and have completed standard frontline radiotherapy.

Detailed Description

Not available

Recruitment & Eligibility

Status
RECRUITING
Sex
All
Target Recruitment
450
Inclusion Criteria
  1. Able to understand the study procedures and agree to participate in the study by providing written informed consent (by participant or legally authorized representative), and assent when applicable.

  2. Body weight ≥ 10 kg at time of randomization.

  3. Histologically diagnosed H3 K27M-mutant diffuse glioma (new diagnosis). Detection of a missense K27M mutation in any histone H3-encoding gene detected by testing of tumor tissue (immunohistochemistry [IHC] or next-generation sequencing [NGS] in a Clinical Laboratory Improvement Amendments [CLIA]-certified or equivalent laboratory). [Site to provide (as available): ≥ 10 unstained formalin-fixed paraffin-embedded (FFPE) slides from tumor tissue.]

  4. At least one, high-quality, contrast-enhanced MRI of the brain obtained prior to starting radiotherapy for submission to sponsor's imaging vendor for central read. For participants who had a surgical resection, this scan must be post-resection; for participants who did not have a resection, this scan may be pre- or post-biopsy.

  5. At least one, high-quality, contrast-enhanced MRI of the brain obtained 2 to 6 weeks after completion of frontline radiotherapy. If unable to obtain contrast-enhanced imaging due to lack of venous access after multiple attempts, a patient may still be eligible after collection of a nonenhanced MRI of the brain. [Site to also provide all available MRIs completed prior to initiating treatment with study intervention.]

  6. Received frontline radiotherapy

    1. Initiated radiotherapy within 12 weeks from the initial diagnosis of H3 K27M-mutant diffuse glioma.
    2. Completed radiotherapy within 2 to 6 weeks prior to randomization
    3. Completed standard fractionated radiotherapy (eg. 54 to 60 Gy in 28 to 33 fractions given over approximately 6 weeks or hypofractionated radiotherapy (eg. 40 Gy in 15 fractions given over approximately 3 weeks).
  7. Karnofsky Performance Status or Lansky Performance Status ≥ 70 at time of randomization.

  8. Stable or decreasing dose of corticosteroids and anti-seizure medications for 7 days prior to randomization, if applicable. Stable steroid dose is defined as ≤ 2 mg/day increase (based on dexamethasone dose or equivalent dose of an alternative steroid).

Exclusion Criteria
  1. Primary spinal tumor.

  2. Diffuse intrinsic pontine glioma (DIPG), defined as tumors with a pontine epicenter and diffuse involvement of the pons.

  3. Evidence of leptomeningeal spread of disease or cerebrospinal fluid dissemination.

  4. Any known concurrent malignancy.

  5. New lesion(s) outside of the radiation field.

  6. Received whole-brain radiotherapy.

  7. Received proton therapy for glioma.

  8. Use of any of the following treatments within the specified time periods prior to randomization:

    1. ONC201 or ONC206 at any time.
    2. Systemic bevacizumab (includes biosimilars) at any time since the initial diagnosis of H3 K27M-mutant diffuse glioma.
    3. Temozolomide within past 3 weeks.
    4. Tumor treating fields at any time.
    5. DRD2 antagonist within past 2 weeks.
    6. Any investigational therapy within past 4 weeks.
    7. Strong CYP3A4 inhibitors within 3 days.
    8. Strong CYP3A4 inducers (includes enzyme-inducing antiepileptic drugs) within 2 weeks.
  9. Laboratory test results meeting any of the following parameters within 2 weeks prior to randomization:

    1. Absolute neutrophil count < 1.0 × 109/L or platelets < 75 × 109/L.
    2. Total bilirubin > 1.5 × upper limit of normal (ULN) (participants with Gilbert's syndrome may be included with total bilirubin > 1.5 × ULN if direct bilirubin is ≤ 1.5 × ULN).
    3. Aspartate aminotransferase (AST) or alanine aminotransferase (ALT) > 2.5 × ULN.
    4. Creatinine clearance ≤ 60 mL/min as calculated by the Cockcroft Gault equation (or estimated glomerular filtration rate < 60 mL/min/1.73 m2).
  10. QTc > 480 msec (based on mean from triplicate electrocardiograms) during screening.

  11. Known hypersensitivity to any excipients used in the study intervention formulation.

  12. Pregnant, breastfeeding, or planning to become pregnant while receiving study intervention or within 3 months after the last dose. Participants of childbearing potential must have a negative serum pregnancy test within 72 hours prior to receiving the first dose of study intervention.

  13. Uncontrolled intercurrent illness including, but not limited to, ongoing or active infection requiring systemic therapy or psychiatric illness/social situations that would limit compliance with study requirements.

  14. Any other condition (eg, medical, psychiatric, or social) that, in the opinion of the investigator, may interfere with participant safety or the ability to complete the study according to the protocol.

Study & Design

Study Type
INTERVENTIONAL
Study Design
PARALLEL
Arm && Interventions
GroupInterventionDescription
ONC201 Twice Weekly GroupDordaviprone (ONC201)-
ONC201 Once Weekly GroupDordaviprone (ONC201) + Placebo-
Placebo GroupPlacebo-
Primary Outcome Measures
NameTimeMethod
Overall survival (OS)From date of randomization until date of death from any cause, assessed up to approximately 44 months

Overall Survival is defined as the time from randomization to death due to any cause.

Progression free survival (PFS) as assessed by using RANO-HGG criteriaFrom date of randomization until the date of first documented progression assessed up to approximately 44 months

PFS is defined as time from randomization to disease progression (PD) or death.

Secondary Outcome Measures
NameTimeMethod
Incidence of adverse eventsFrom date of randomization up to 44 months

Incidence of overall, treatment-related, Grade 3 or higher in severity, serious, fatal, those resulting in treatment discontinuation, and events of special interest

Change from baseline in clinical laboratory parametersFrom date of randomization up to 44 months

Percentage of participants with clinically significant laboratory results

PFS using RANO-HGG criteriaFrom date of randomization up to 44 months

PFS using RANO-HGG criteria for participants with measurable contrast-enhancing disease

Corticosteroid responseFrom date of randomization up to 44 months

Corticosteroid response will be measured by a confirmed 50% decrease in use of dexamethasone or equivalent

Performance status responseFrom date of randomization up to 44 months

Performance status response will be measured by confirmed increase in Karnofsky Performance Status (KPS) or Lansky Performance Status (LPS)

Trial Locations

Locations (156)

Churchill Hospital

🇬🇧

Oxford, United Kingdom

Barrow Neurological Institute

🇺🇸

Phoenix, Arizona, United States

Banner MD Anderson Cancer Center

🇺🇸

Phoenix, Arizona, United States

Phoenix Childrens Hospital

🇺🇸

Phoenix, Arizona, United States

Mayo Clinic Arizona

🇺🇸

Phoenix, Arizona, United States

University of California Irvine

🇺🇸

Costa Mesa, California, United States

UC San Diego Moores Cancer Center

🇺🇸

La Jolla, California, United States

Kaiser Permanente Los Angeles Medical Center

🇺🇸

Los Angeles, California, United States

UCLA University of California Los Angeles

🇺🇸

Los Angeles, California, United States

Children's Hospital of Orange County

🇺🇸

Orange, California, United States

UCSF Benioff Children's Hospital

🇺🇸

San Francisco, California, United States

University of California San Francisco

🇺🇸

San Francisco, California, United States

Providence Saint John's Cancer Institute

🇺🇸

Santa Monica, California, United States

Stanford Cancer Center

🇺🇸

Stanford, California, United States

Yale University

🇺🇸

Fairfield, Connecticut, United States

MedStar Georgetown University Hospital

🇺🇸

Washington, District of Columbia, United States

Mayo Clinic Jacksonville

🇺🇸

Jacksonville, Florida, United States

Miami Cancer Institute

🇺🇸

Miami, Florida, United States

St Joseph's Children's Hospital of Tampa

🇺🇸

Tampa, Florida, United States

Moffitt Cancer Center

🇺🇸

Tampa, Florida, United States

Children's Healthcare of Atlanta

🇺🇸

Atlanta, Georgia, United States

Kapi'olani Medical Center for Women and Children

🇺🇸

Honolulu, Hawaii, United States

Feinberg School of Medicine Northwestern University

🇺🇸

Chicago, Illinois, United States

Indiana University School of Medicine - Indianapolis

🇺🇸

Indianapolis, Indiana, United States

University of Iowa Hospitals & Clinics

🇺🇸

Iowa City, Iowa, United States

Norton Healthcare

🇺🇸

Louisville, Kentucky, United States

Ochsner Medical Center - New Orleans

🇺🇸

New Orleans, Louisiana, United States

University of Maryland School of Medicine

🇺🇸

Baltimore, Maryland, United States

Massachusetts General Hospital Cancer Center

🇺🇸

Boston, Massachusetts, United States

Dana Farber Cancer Institute

🇺🇸

Boston, Massachusetts, United States

University of Michigan Hospital

🇺🇸

Ann Arbor, Michigan, United States

University of Minnesota

🇺🇸

Minneapolis, Minnesota, United States

Mayo Clinic - Cancer Center - Rochester

🇺🇸

Rochester, Minnesota, United States

Washington University School of Medicine

🇺🇸

Saint Louis, Missouri, United States

Benefis Hospital Sletten Cancer Institute

🇺🇸

Great Falls, Montana, United States

University of Nebraska Medical Center

🇺🇸

Omaha, Nebraska, United States

Jersey Shore University Medical Center

🇺🇸

Neptune, New Jersey, United States

Overlook Medical Center

🇺🇸

Summit, New Jersey, United States

Albany Medical Center

🇺🇸

Albany, New York, United States

Children's Hospital at Montefiore Medical Center

🇺🇸

New York, New York, United States

Montefiore Medical Park

🇺🇸

New York, New York, United States

Laura & Isaac Perlmutter Cancer Center - NYU ACC

🇺🇸

New York, New York, United States

Columbia University Medical Center

🇺🇸

New York, New York, United States

Lenox Hill Hospital

🇺🇸

New York, New York, United States

University of Rochester Medical Center

🇺🇸

Rochester, New York, United States

Levine Cancer Institute/ Atrium Health

🇺🇸

Charlotte, North Carolina, United States

Duke Cancer Institute

🇺🇸

Durham, North Carolina, United States

Cincinnati Children's Hospital Medical Center

🇺🇸

Cincinnati, Ohio, United States

Cleveland Clinic

🇺🇸

Cleveland, Ohio, United States

Ohio State University

🇺🇸

Columbus, Ohio, United States

University of Oklahoma Peggy and Charles Stephenson Cancer Center

🇺🇸

Oklahoma City, Oklahoma, United States

Providence Health and Services St. Vincent Medical Center

🇺🇸

Portland, Oregon, United States

University of Pennsylvania

🇺🇸

Philadelphia, Pennsylvania, United States

Thomas Jefferson University

🇺🇸

Philadelphia, Pennsylvania, United States

UPMC Children's Hospital of Pittsburgh

🇺🇸

Pittsburgh, Pennsylvania, United States

UPMC Hillman Cancer Center

🇺🇸

Pittsburgh, Pennsylvania, United States

Dell Children's Medical Center of Central Texas

🇺🇸

Austin, Texas, United States

Neuro-Oncology Associates

🇺🇸

Dallas, Texas, United States

University of Texas Southwestern Medical Center

🇺🇸

Dallas, Texas, United States

University of Texas MD Anderson Cancer Center

🇺🇸

Houston, Texas, United States

UT Health Science Center Houston Department of Neurosurgery

🇺🇸

Houston, Texas, United States

University of Texas - San Antonio - Health Science Center

🇺🇸

San Antonio, Texas, United States

University of Utah - Huntsman Cancer Institute

🇺🇸

Salt Lake City, Utah, United States

Inova Schar Cancer Institute

🇺🇸

Fairfax, Virginia, United States

Children's Hospital of The King's Daughter

🇺🇸

Norfolk, Virginia, United States

University of Washington

🇺🇸

Seattle, Washington, United States

University Of Wisconsin - Madison

🇺🇸

Madison, Wisconsin, United States

FLENI Neurologia

🇦🇷

Ciudad Autónoma de Buenos Aires, Argentina

Sydney Children's Hospital

🇦🇺

Randwick, New South Wales, Australia

Royal North Shore Hospital

🇦🇺

Sydney, New South Wales, Australia

Royal Brisbane and Women's Hospital

🇦🇺

Herston, Queensland, Australia

Royal Hobart Hospital

🇦🇺

Hobart, Tasmania, Australia

Olivia Newton-John Cancer Research Institute (ONJCRI)

🇦🇺

Heidelberg, Victoria, Australia

Perth Children's Hospital

🇦🇺

Nedlands, Western Australia, Australia

Medical University of Vienna - Adults

🇦🇹

Vienna, Wien, Austria

Medical University of Vienna - Pediatrics

🇦🇹

Vienna, Wien, Austria

Hospital do GRAACC

🇧🇷

São Paulo, Brazil

Tom Baker Cancer Cetre

🇨🇦

Calgary, Alberta, Canada

BC Cancer - The Vancouver Center

🇨🇦

Vancouver, British Columbia, Canada

Children's & Women's Health Care of BC

🇨🇦

Vancouver, British Columbia, Canada

London Health Sciences Centre

🇨🇦

London, Ontario, Canada

Childrens Hospital of Eastern Ontario

🇨🇦

Ottawa, Ontario, Canada

Sunnybrook Health Sciences Centre

🇨🇦

Toronto, Ontario, Canada

Princess Margaret Hospital

🇨🇦

Toronto, Ontario, Canada

Hopital Notre Dame, Lachapelle

🇨🇦

Montréal, Quebec, Canada

Copenhagen University Hospital

🇩🇰

Copenhagen, Capital, Denmark

Aalborg Universitetshospital

🇩🇰

Aalborg, Nordjylland, Denmark

F345 H.C. Andersen's Children's Hospital

🇩🇰

Odense, South Denmark, Denmark

Odense Universitetshospital

🇩🇰

Odense, South Denmark, Denmark

University Clinic Heidelberg

🇩🇪

Heidelberg, Baden-Württemberg, Germany

Universitätsklinikum Heidelberg

🇩🇪

Heidelberg, Baden-Württemberg, Germany

Universitätsklinikum Augsburg

🇩🇪

Augsburg, Bayern, Germany

University Clinic Regensburg

🇩🇪

Regensburg, Bayern, Germany

Klinikum der Johann-Wolfgang Goethe-Universitat

🇩🇪

Frankfurt am Main, Hessen, Germany

Universitätsklinikum Bonn

🇩🇪

Bonn, Nordrhein-Westfalen, Germany

Universitätsklinikum Essen

🇩🇪

Essen, Nordrhein-Westfalen, Germany

Uniklinik Köln

🇩🇪

Köln, Nordrhein-Westfalen, Germany

Vivantes Klinikum Neukölln

🇩🇪

Berlin, Germany

Klinikum Mannheim Universitätsklinikum gGmbH

🇩🇪

Manheim, Germany

Universitätsklinikum Tübingen

🇩🇪

Tübingen, Germany

Queen Mary Hospital

🇭🇰

Hong Kong, Hong Kong

Sheba Medical Center

🇮🇱

Ramat Gan, Tel-Aviv, Israel

Soroka University Medical Centre

🇮🇱

Be'er Sheva, Israel

Rambam Medical Center

🇮🇱

Haifa, Israel

Hadassah Ein Kerem Medical Center

🇮🇱

Jerusalem, Israel

Schneider Children's Medical Center of Israel

🇮🇱

Petah Tikvah, Israel

Rabin Medical Center

🇮🇱

Petah Tikva, Israel

Tel Aviv Sourasky Medical Center

🇮🇱

Tel Aviv, Israel

Ospedale Bellaria

🇮🇹

Bologna, Emilia-Romagna, Italy

Istituto Nazionale Tumori Regina Elena

🇮🇹

Roma, Lazio, Italy

Ospedale San Raffaele S.r.l.

🇮🇹

Milano, Lombardia, Italy

Fondazione IRCCS Di Rilievo Nazionale Istituto Nazionale Neurologico Carlo Besta

🇮🇹

Milano, Lombardia, Italy

Istituto Clinico Humanitas

🇮🇹

Rozzano, Lombardia, Italy

Azienda Ospedaliera Città della Salute e della Scienza di Torino

🇮🇹

Torino, Piemonte, Italy

Istituto Oncologico Veneto

🇮🇹

Padova, Veneto, Italy

National Cancer Center Hospital

🇯🇵

Chuo City, Japan

National Hospital Organization Kyushu Cancer Center

🇯🇵

Fukuoka, Japan

Kyoto University Hospital

🇯🇵

Kyoto, Japan

Osaka City General Hospital

🇯🇵

Osaka, Japan

Hokkaido University Hospital

🇯🇵

Sapporo, Japan

CHA Bundang Medical Center

🇰🇷

Bundang-Gu, Seongnam-Si, Gyeonggido, Korea, Republic of

Seoul National University Bundang Hospital

🇰🇷

Bundang-gu, Seongnam-si, Gyeonggido, Korea, Republic of

National Cancer Center

🇰🇷

Ilsandong-Gu, Goyang-Si, Gyeonggido, Korea, Republic of

Samsung Medical Center

🇰🇷

Gangnam-Gu, Seoul Teugbyeolsi, Korea, Republic of

Gangnam Severance Hospital, Yonsei University Health System

🇰🇷

Gangnam, Seoul Teugbyeolsi, Korea, Republic of

Seoul National University Hospital

🇰🇷

Jongno-Gu, Seoul Teugbyeolsi, Korea, Republic of

Asan Medical Center

🇰🇷

Seoul, Seoul Teugbyeolsi, Korea, Republic of

Severance Hospital Yonsei University Health System

🇰🇷

Seoul, Korea, Republic of

The Catholic University of Korea, Seoul St. Mary's Hospital

🇰🇷

Seoul, Korea, Republic of

Erasmus MC

🇳🇱

Rotterdam, Zuid-Holland, Netherlands

Universitair Medisch Centrum Utrecht Cancer Center

🇳🇱

Utrecht, Netherlands

KK Women's and Children's Hospital

🇸🇬

Singapore, Singapore

National Cancer Centre

🇸🇬

Singapore, Singapore

National Neuroscience Institute

🇸🇬

Singapore, Singapore

Hospital Sant Joan de Deu

🇪🇸

Esplugues De Llobregat, Barcelona, Spain

Clinica Universidad Navarra

🇪🇸

Pamplona, Navarra, Spain

Hospital Clinic de Barcelona

🇪🇸

Barcelona, Spain

Hospital Universitario Vall d'Hebron

🇪🇸

Barcelona, Spain

Hospital Infantil Universitario Niño Jesus

🇪🇸

Madrid, Spain

Hospital Universitario 12 de Octubre

🇪🇸

Madrid, Spain

Hospital Universitario HM Sanchinarro

🇪🇸

Madrid, Spain

Complejo Asistencial Universitario de Salamanca - H. Clinico

🇪🇸

Salamanca, Spain

Hospital Universitari i Politecnic La Fe de Valencia

🇪🇸

Valencia, Spain

Centre Hospitalier Universitaire Vaudois

🇨🇭

Lausanne, Vaud, Switzerland

Universitätsspital Zürich

🇨🇭

Zürich, Switzerland

Addenbrooke's Hospital

🇬🇧

Cambridge, Cambridgeshire, United Kingdom

Beatson West of Scotland Cancer Centre

🇬🇧

Glasgow, Lanarkshire, United Kingdom

Royal Hospital for Children (Glasgow)

🇬🇧

Glasgow, Lanarkshire, United Kingdom

Clatterbridge Cancer Centre - Liverpool

🇬🇧

Liverpool, Lancashire, United Kingdom

The Christie NHS Foundation Trust

🇬🇧

Manchester, Lancashire, United Kingdom

The Royal Marsden in Sutton, Surrey

🇬🇧

Sutton, Surrey, United Kingdom

Royal Victoria Infirmary

🇬🇧

Newcastle Upon Tyne, Tyne And Wear, United Kingdom

Freeman Hospital

🇬🇧

Newcastle Upon Tyne, Tyne And Wear, United Kingdom

St James University Hospital

🇬🇧

Leeds, West Yorkshire, United Kingdom

The Leeds Teaching Hospitals NHS Trust, Leeds General Infimary

🇬🇧

Leeds, United Kingdom

Guy's Hospital

🇬🇧

London, United Kingdom

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