MedPath

Arginine Therapy for the Treatment of Pain in Children With Sickle Cell Disease

Phase 1
Recruiting
Conditions
Sickle Cell Disease
Interventions
Registration Number
NCT02447874
Lead Sponsor
Emory University
Brief Summary

The purpose of this study is to determine whether giving extra arginine to patients with sickle cell disease seeking treatment for vaso-occlusive painful events (VOE) will decrease pain scores, decrease need for pain medications or decrease length of hospital stay or emergency department visit.

Detailed Description

Arginine is a simple amino acid that is found in many foods and is part of the proteins in a human's body. Patients with sickle cell disease have low levels of the amino acid arginine and these low levels may be related to pain episodes. Increasing levels of arginine in the blood may lower pain and/or lower the amount of pain medication (like morphine) that is needed to treated them. It may also decrease the amount of time spent in the hospital.

Available data suggest that, L-arginine is a safe \& efficacious intervention with narcotic-sparing effects in pediatric SCD patients with VOE. The addition of a higher loading dose to the standard dose or use of a continuous infusion may provide additional clinical benefits by overcoming multiple mechanisms that limit global arginine bioavailability in SCD.

Recruitment & Eligibility

Status
RECRUITING
Sex
All
Target Recruitment
21
Inclusion Criteria
  • Established diagnosis of sickle cell disease--Hemoglobin SS (Hb-SS) or Sβᴼ-thalassemia
  • 7-21 years of age
  • Weight >= 25kg (55lbs)
  • Pain requiring medical care in an acute care setting (emergency department (ED), hospital ward, day hospital, clinic) requiring parenteral opioids, not attributable to non-sickle cell causes.
Exclusion Criteria
  • Decision to discharge home from acute care setting.
  • Diagnosis of sickle cell disease with any of the following types: hemoglobin SC disease (HbSC), hemoglobin beta thalassemia (Hb-Beta Thal), hemoglobin SD disease (HbSD), hemoglobin SE disease (HbSE), hemoglobin SO disease (HbSO), hemoglobin AS carrier (Hb AS)
  • Hemoglobin less than 5 gm/dL
  • Immediate Red cell transfusion anticipated
  • Renal dysfunction: Creatinine >1.0 or 2 x baseline
  • Mental status or neurological changes
  • Acute stroke or clinical concern for stroke
  • Pregnancy
  • Allergy to arginine
  • Previous hospitalization < 7 days
  • Use of inhaled nitric oxide, sildenafil or arginine within the last 14 days
  • Not an appropriate candidate in the investigator's judgement

Study & Design

Study Type
INTERVENTIONAL
Study Design
CROSSOVER
Arm && Interventions
GroupInterventionDescription
Loading dose + standard doseArginine (Loading)Subjects with sickle cell disease and vaso-occlusive painful events (VOE) will be randomized to receive an intravenous (IV) infusion of an initial loading dose of arginine (200 mg/kg) given over 30 minutes and then receive an intravenous (IV) infusion of a standard dose of arginine (100 mg/kg) three times a day for seven days or until discharged from the hospital, whichever occurs first
Non-Randomized Loading dose 500 mg/kg + standard doseArginine (Loading)Arginine will be dispensed intravenously (in the vein) as an initial bolus (loading) arginine dose at 500 mg/kg once, followed by a standard dose of 100mg/kg every 8 hours until discharge or for a total of 21 doses of arginine, whichever comes first.
Non-Randomized Loading dose 300 mg/kg + standard doseArginine (Loading)Arginine will be dispensed intravenously (in the vein) as an initial bolus (loading) arginine dose at 300 mg/kg once, followed by a standard dose of 100mg/kg every 8 hours until discharge or for a total of 21 doses of arginine, whichever comes first.
Non-Randomized Loading dose 400mg/kg + standard doseArginine (Loading)Arginine will be dispensed intravenously (in the vein) as an initial bolus (loading) arginine dose at 400 mg/kg once, followed by a standard dose of 100mg/kg every 8 hours until discharge or for a total of 21 doses of arginine, whichever comes first.
Loading dose + continuous infusionArginine (Loading)Subjects with sickle cell disease and vaso-occlusive painful events (VOE) will be randomized to receive an intravenous (IV) infusion of an initial loading dose of arginine (200 mg/kg) given over 30 minutes and then receive a continuous intravenous (IV) infusion of 300 mg/kg/24hr for 7 days or until discharged from the hospital, whichever occurs first
Loading dose + continuous infusionArginine (Continuous)Subjects with sickle cell disease and vaso-occlusive painful events (VOE) will be randomized to receive an intravenous (IV) infusion of an initial loading dose of arginine (200 mg/kg) given over 30 minutes and then receive a continuous intravenous (IV) infusion of 300 mg/kg/24hr for 7 days or until discharged from the hospital, whichever occurs first
Standard doseArginineSubjects with sickle cell disease (SCD) and vaso-occlusive painful events (VOE) will be randomized to receive an intravenous (IV) infusion of a standard dose of arginine (100 mg/kg) three times a day for seven days or until discharged from the hospital, whichever occurs first
Loading dose + standard doseArginineSubjects with sickle cell disease and vaso-occlusive painful events (VOE) will be randomized to receive an intravenous (IV) infusion of an initial loading dose of arginine (200 mg/kg) given over 30 minutes and then receive an intravenous (IV) infusion of a standard dose of arginine (100 mg/kg) three times a day for seven days or until discharged from the hospital, whichever occurs first
Primary Outcome Measures
NameTimeMethod
Pharmacokinetics of IV arginine, measured by plasma arginine concentration over timeDay 1 through study completion, an average of up to 7 days

Total time plasma arginine levels are maintained above the half-saturating concentration (Km) of cationic amino acid transporter protein-1 (CAT-1), which is 150 µM (normal range of extracellular plasma arginine concentration). pK samples will be collected at 6 time-points within 8 hours: prior to arginine treatment (time 0), and at 60, 90, 120 minutes, 4 and 8 hours after the initiation of arginine therapy, and then every 24 hours up to 7 days.

Change in nitric oxide metabolitesBaseline, day 1 through study completion, an average of up to 7 days

The formation of NO metabolites will be measured by determination of its stable end products in serum; nitrite (NO2-) and nitrate (NO3-). Change in nitric oxide metabolites will be calculated as the difference in metabolites from the time prior to arginine treatment (baseline) to the end of the intervention period.

Secondary Outcome Measures
NameTimeMethod
Area Under the Plasma Concentration -Time Curve (AUC) From Time 0 to the Time of the Last Quantifiable Concentration for ArginineDay 1

AUC is derived from drug concentration and time so it gives a measure of how much and how long a drug stays in a body. AUC(0-tlqc) is a measure of total plasma exposure to the drug from Time 0 to Time of the Last Quantifiable Concentration (AUC\[0-tlqc\])

Maximum observed plasma concentration of arginineDay 1

Maximum measured concentration of the arginine in plasma

Apparent clearance of arginineDay 1

The clearance of a drug measures the rate at which the drug is removed from the body after the dose. Clearance of arginine after intravenous administration on day 1.

Change in red blood cell (RBC) arginineBaseline, day 1 through study completion, an average of up to 7 days

Change in rbc arginine will be calculated as rbc arginine at the end of arginine administration minus rbc arginine at baseline.

Change in asymmetric dimethylarginine (ADMA) levelsBaseline, day 1 and through study completion, an average of up to 7 days

ADMA is is a metabolic by-product of continual protein modification processes and interferes with L-arginine in the production of nitric oxide. Change in ADMA levels will be calculated as ADMA levels at the end of arginine administration minus ADMA levels at baseline.

Modeling nitric oxide (NOx) level versus plasma arginine levelFrom enrollment through study completion, an average of up to 7 days

Modeling nitric oxide (NOx) level versus plasma arginine level will be measured.

Biomarkers of hemolysisFrom enrollment through study completion, an average of up to 7 days

Biomarkers of hemolysis (lactate dehydrogenase, hemoglobin, reticulocytes, arginase, indirect bilirubin) represent intravascular hemolysis and nitric oxide bioavailability.

Level of cytokinesFrom enrollment through study completion, an average of up to 7 days

Cytokines are biomarkers for inflammation. Cell supernatants will be collected and analyzed for different cytokines.

Erythrocyte glutathione levelsFrom enrollment through study completion, an average of up to 7 days

Erythrocyte glutathione is a biomarker for oxidative stress. It will be measured by using liquid chromatography.

Terminal elimination half-life (t1/2) for arginineDay 1

Terminal phase elimination half-life (t1/2) is the time required for half of the drug to be eliminated from the plasma.

Daily urine arginineFrom Day 1 until study completion, an average of up to 7 days

Total amount of arginine excreted in urine daily

Global arginine bioavailability (GABR)From enrollment through study completion, an average of up to 7 days

GABR represents a measure of endothelial function. GABR will be calculated by arginine divided by the sum of ornithine plus citrulline \[arginine/(ornithine+citrulline)\].

Trial Locations

Locations (2)

Children's Healthcare fo Atlanta at Hughes Spalding

🇺🇸

Atlanta, Georgia, United States

Children's Healthcare of Atlanta at Egleston

🇺🇸

Atlanta, Georgia, United States

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