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Combination of an Anti-PD1 Antibody With Tisagenlecleucel Reinfusion in Children, Adolescents and Young Adults With Acute Lymphoblastic Leukemia After Loss of Persistence

Phase 1
Recruiting
Conditions
B Acute Lymphoblastic Leukemia
Acute Lymphoblastic Leukemia, in Relapse
Interventions
Drug: Decreasing starting times for beginning nivolumab (Time to Event Continual Reassessment Method (TITE-CRM) )
Registration Number
NCT05310591
Lead Sponsor
Assistance Publique - Hôpitaux de Paris
Brief Summary

Tisagenlecleucel (CTL019) is an anti-CD19 autologous Chimeric Antigen Receptor (CAR) T-cell therapy, which has shown dramatic early results in advanced ALLs. Early loss of B-cell aplasia (recovery of B-cells in marrow/ peripheral blood within 6 months after infusion), a marker of the loss or non-functionality of the CAR T-cells, is associated to a very high risk of relapse. A reinfusion of CTL019, even after Fludarabine-Cyclophosphamide reconditioning, frequently fails to induce further expansion as observed in UPENN studies and in the Robert Debré Hospital experience.

Non-persistence of CAR T-cells may be due to immune- mediated rejection or environment-mediated suppression of their growth. Evidence for increased PD-1 expression in CAR T-cells between infusion and peak expansion has been demonstrated in clinical samples.

Preclinical data and few clinical data support a role of PD- 1-PD-L1 blockade in improving the effectiveness of CAR T-cell therapy.

The objectives of this phase I/II study is to determine the safety, efficacy and feasibility of Nivolumab (Opdivo®)- an anti-PD1 treatment- combined to tisagenlecleucel in a cohort of relapsed or refractory B-ALL patients, aged 1-25 years old, previously treated by tisagenlecleucel (Kymriah®), with a demonstrated early loss of B-cell aplasia (within 6 months), a surrogate marker of the loss of CAR T-cells or their non- functionality.

More specifically, the main objectives are:

• In cohort 1 that includes patients with a MRD negative disease status combined to an early loss (within 6 months) of B-cell aplasia :

To determine the optimal starting time of Nivolumab (Opdivo®) in terms of safety and efficacy among 4 candidate time points (day 14, day 11, day 5, and day - 1).

• In cohort 2 that includes relapsed patients with an early loss (within 6 months) of B-cell aplasia :

To estimate the feasibility in terms of safety and efficacy of a very early start of nivolumab (day-1), prior to the reinfusion of tisagenlecleucel

Detailed Description

Not available

Recruitment & Eligibility

Status
RECRUITING
Sex
All
Target Recruitment
26
Inclusion Criteria
  • Patients aged from 1 to 25 years (pediatric and young adults) with a history of CD19+ relapsed or refractory B-ALL (any relapse after HSCT, 2nd relapse or later, refractory ALL).
  • Patient must have a second tisagenlecleucel (Kymriah ®) product available
  • Cohort 1: previously treated by tisagenlecleucel (Kymriah ®), and who present an early loss of B-cell aplasia defined by blood B lymphocytes < 10 /mm3 and/ or < 3% of total lymphocytes (< 6 months after infusion) while still being in CR with undetectable MRD
  • Cohort 2: previously treated by tisagenlecleucel (Kymriah ®), who present a loss of B-cell aplasia defined by blood B lymphocytes < 10 /mm3 and/ or < 3% of total lymphocytes and a CD19+ ALL detectable disease in the marrow and/or Blood
  • Life expectancy > 12 weeks.
  • Karnofsky (age > 16) Lansky (age < 16) > 70 at screening.
  • No organ dysfunction
  • Who have signed an informed consent
  • Affiliation to social security or any health insurance (as a beneficiary or assignee)
Exclusion Criteria
  • Patient has received intervening therapy for leukemia after first tisagenlecleucel infusion (chemotherapy, anti leukemic immunotherapy, ITK, allogeneic HSCT).

  • Patient has an active autoimmune disease requiring systemic treatment within the past 2 years.

  • Patient has known history of, or any evidence of active, non-infectious pneumonitis.

  • Patient has a history of non-infectious pneumonitis that required steroid or has current pneumonitis.

  • Had receive prior therapy with an anti-PD1, Anti- PDL1 or anti-PDL2 agent.

  • Patient has hypersensivity to pembrolizumab/ nivolumab or one of its excipients

  • Patient has received a live vaccine injection within 45 days of planned start of study therapy.

  • Patients with concomitant genetic syndromes associated with bone marrow failure states: such as patients with Fanconi anemia, Kostmann syndrome, Shwachman syndrome or any other known bone marrow failure syndrome. Patients with Down syndrome will not be excluded.

  • Patients with Burkitt's lymphoma/leukemia

  • Prior malignancy, except carcinoma in situ of the skin or cervix treated with curative intent and with no evidence of active disease.

  • Prior treatment with any gene therapy product except first tisagenlecleucel (Kymriah ®) injection.

  • Prior treatment with any anti-CD19/anti-CD3 therapy, or any other anti-CD19 therapy, except for patients pre-treated with blinatumomab and/or tisagenlecleucel (Kymriah®)

  • Prior anti-cancer monoclonal antibody within 4 weeks before starting the study.

  • Prior chemotherapy, targeted small molecule therapy, or radiation therapy within 2 weeks prior to study Day 1 or who has not recovered (i.e., ≤ Grade1 or at baseline) from adverse events due to a previously administered agent.

  • Active or latent hepatitis B or active hepatitis C (test within 8 weeks of Screening), or any uncontrolled infection at Screening.

  • Human immunodeficiency virus (HIV) positive test within 8 weeks of Screening.

  • Presence of grade 2 to 4 acute or extensive chronic GVHD.

  • Active CNS involvement by malignancy, defined as CNS-3 per NCCN guidelines. Note: Patients with history of CNS disease that has been effectively treated will be eligible.

  • Uncontrolled acute life threatening bacterial, viral or fungal infection at Screening.

  • Previous or concurrent malignancy with the following exceptions:

    • Adequately treated basal cell or squamous cell carcinoma
    • in situ carcinoma of the cervix or breast, treated curatively and without evidence of recurrence for at least 3 years prior to the study.
    • A primary malignancy completely resected and in CR for ≥ 5 years
  • Pregnant or lactating women (female study participants of reproductive potential must have a negative serum or urine pregnancy test performed within 48 hours before infusion)

  • Patient with hypersensivity to Fludarabine and/or cyclophosphamide and/or tisagenlecleucel and/or nivolumab or one of their excipients.

Study & Design

Study Type
INTERVENTIONAL
Study Design
SINGLE_GROUP
Arm && Interventions
GroupInterventionDescription
For relapsed patientsNivolumab starting at day -1-
Patients with MRD negative disease status: Time to Event Continual Reassessment Method (TITE-CRM)Decreasing starting times for beginning nivolumab (Time to Event Continual Reassessment Method (TITE-CRM) )-
Primary Outcome Measures
NameTimeMethod
Efficacy assessed by Minimal residual disease (MRD) negative Complete remission (CR) and B cell aplasia.at 3 months

MRD negative CR is defined by undetectable disease at a 10-4 sensitivity threshold B cell aplasia is defined by blood B lymphocytes \< 10 /mm3 and/or \< 3% of total lymphocytes

Proportion of patients with limiting-toxicitiesat day 28

Limiting toxicities are defined by the occurrence of either

- Related to CAR-T cells infusion: CRS or aGVH: limiting toxicity will be defined as toxicity ≥ 4 ICANs: limiting toxicity will be defined as toxicity ≥ 3 (excepted grade 3 seizure, ie focal, generalized seizure that resolves rapidly)

- Related to nivolumab: immune related myocarditis, pneumonitis, encephalitis: limiting toxicity will be defined as toxicity ≥ 4

Secondary Outcome Measures
NameTimeMethod
Incidence of Grade 3, 4 or 5 nivolumab-related adverse eventsup to 2 years
Proportion of patients with Minimal residual diseaseat 12 months
Incidence of B cell aplasiaat 6 months
Proportion of patients with Disease best responseup to three months
Overall survivalat 2 years
Proportion of patients with Complete remissionat 12 months
Incidence of GVHDup to one year
Incidence of Grade 3 adverse eventsup to 2 years
Increase of B cell aplasia duration compared to the previous one observedup to 24 months
Event Free Survival (EFS)at 2 years

Trial Locations

Locations (12)

HCL - Lyon Sud

🇫🇷

Lyon, France

CHU Nancy

🇫🇷

Nancy, France

CHU Nantes - Hopital Mère-enfants

🇫🇷

Nantes, France

CHU Rouen

🇫🇷

Rouen, France

CHRU Bordeaux

🇫🇷

Bordeaux, France

HCL

🇫🇷

Lyon, France

CHRU Lille

🇫🇷

Lille, France

Hôpital pour enfants - La Timone

🇫🇷

Marseille, France

CHU Montpellier - Hopital Arnaud de Villeneuve

🇫🇷

Montpellier, France

Robert Debre hospital

🇫🇷

Paris, France

Saint Louis hospital

🇫🇷

Paris, France

CHRU Strasbourg

🇫🇷

Strasbourg, France

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