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Clinical Trials/2023-507010-27-00
2023-507010-27-00
Recruiting
Phase 3

CUSHMAH - Benefit of steroidogenesis inhibitors in Mild Cushing syndrome (Mild Autonomous Cortisol Secretion): a randomized trial in patients with Primary Bilateral Macronodular Adrenocortical Hyperplasia

Assistance Publique Hopitaux De Paris13 sites in 1 country70 target enrollmentStarted: September 1, 2026Last updated:

Overview

Phase
Phase 3
Status
Recruiting
Enrollment
70
Locations
13
Primary Endpoint
At 6 months of treatment number of patients achieving: 1) improvement of blood pressure control and/or 2) improvement of diabetes

Overview

Brief Summary

Demonstrate that cortisol secretion inhibition by medical treatment (metyrapone) in PBMAH patients with MACS lead to improvement of hypertension and diabetes.

Eligibility Criteria

Ages
18 years to 65+ years (18-64 Years, 65+ Years)
Accepts Healthy Volunteers
No

Inclusion Criteria

  • Age ≥ 18 years old
  • French speaking
  • Patient with PBMAH as determined by adrenal imaging (CT-scan and/or MRI) showing multiples bilateral supracentrimetric adrenal nodules
  • Mild autonomous cortisol secretion: plasma cortisol after 1 mg overnight dexamethasone test > 50 nmol/L, 24 h Urinary free cortisol < 1,5 upper limit of Normal
  • Adrenal origin of cortisol excess: morning plasma ACTH < 10 pg/ml or between 10 and 20 pg/ml non responsive to CRH stimulation (stimulation < 50 %)
  • Hypertension (systolic blood pressure > 140 mmHg or diastolic blood pressure > 90 mmHg) or treated hypertension and/or diabetes that can be treated with antidiabetic treatments (WHO criteria)
  • For women of childbearing potential (WOCBP), negative bHCG and highly effective contraception
  • For male, an effective method of contraception
  • Signed a written informed consent
  • Affiliated to social security regime or an equivalent system

Exclusion Criteria

  • Patients with a Cushing syndrome from another causes than PBMAH
  • Pregnancy or breastfeeding women
  • Steroidogenesis inhibitor treatment less than 6 weeks before inclusion
  • Pathology that is life-threatening in the short term (1 year)
  • Patients with major psychiatric disorders that may interfere with the smooth running of the study
  • Patients on AME (state medical aid)
  • Participation to another clinical trial on medicinal products for human use
  • Patients with proven primary adrenal insufficiency
  • Under glucocorticoid (systemic or high dose local) treatment
  • Contraindication to steroidogenesis inhibitor

Arms & Interventions

METYRAPONE ESTEVE 250 mg, capsule molle

Test

Intervention: METYRAPONE ESTEVE 250 mg, capsule molle (Drug)

Placebo of metyrapon 250 mg

Placebo

Intervention: Placebo of metyrapon 250 mg (Drug)

Outcomes

Primary Outcomes

At 6 months of treatment number of patients achieving: 1) improvement of blood pressure control and/or 2) improvement of diabetes

At 6 months of treatment number of patients achieving: 1) improvement of blood pressure control and/or 2) improvement of diabetes

Secondary Outcomes

  • Change of urinary cortisol, salivary cortisol during the circadian rhythm, steroid profile (mass spectrometry analysis) and morning ACTH plasma level at M0, M3 and M6
  • Evolution of Body Mass Index, insulin sensitivity as determined by HOMA, glycemia as determined by glucose continuous monitoring, total cholesterol, HDL, LDL, triglyceride at M0, M3 and M6
  • Mean change from baseline to M6 in day-time and night-time Systolic and Diastolic Blood Pressure irrespective of antihypertensive treatment adaptations
  • Mean change from baseline to M6 in HbA1c irrespective of antidiabetic treatment adaptations
  • Change in the score of the 3 following quality of life and depression questionnaires at M0, M3 and M6: Medical Outcomes Study 36-item short-form health survey (SF-36), the Beck depression inventory (BECK BDI-II) and the QolCushing
  • Comparaison of the hormonal and clinical response according to the ARMC5, PDE11A4 and NR3C1 genotypes.
  • Collecting data on adverse events

Investigators

Sponsor Class
Hospital/Clinic/Other health care facility
Responsible Party
Principal Investigator
Principal Investigator

Pr Jérôme BERTHERAT (Coordinating investigator)

Scientific

Assistance Publique Hopitaux De Paris

Study Sites (13)

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