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MRI Study - Chronic Progressive External Ophthalmoplegia

Completed
Conditions
Chronic Progressive External Ophthalmoplegia
Interventions
Other: Magnetic Resonance Imaging
Registration Number
NCT02161848
Lead Sponsor
Rigshospitalet, Denmark
Brief Summary

The purpose of this study is to investigate the fraction of fat on a MRI scan of lower bag muscles, thighs and calves in patients with the mitochondrial disease chronic progressive external ophthalmoplegia (CPEO).

Additionally an investigation of the volume of the eye muscles will be done and compared to the patient's clinical presentation of ptosis and ophthalmoplegia.

Detailed Description

The lack of energy and fatigue seen in patients with mitochondrial diseases have been assumed to be caused by an energy defect because of a genetic defect in the mitochondrial DNA.

The investigators have analyzed a few MRI scans of muscles from patients with CPEO and have seen an extended amount of fat in their muscles, which seems to progress with age. The patient's symptoms might be caused by the extended amount of fat and thereby a less amount of active muscle instead of the "energy defect".

This will be investigated in a group of patients with CPEO and the results will be compared with results from a group of healthy controls.

Recruitment & Eligibility

Status
COMPLETED
Sex
All
Target Recruitment
133
Inclusion Criteria
  • Danish patients with verified single large-scale mtDNA deletions and chronic progressive external ophthalmoplegia.
Exclusion Criteria
  • Patients who have metal implants in the body, for instance surgical clips, cochlear implant, pacemaker etc.
  • Patients who are pregnant or breast-feeding.
  • Patients who are claustrophobic

Study & Design

Study Type
OBSERVATIONAL
Study Design
Not specified
Arm && Interventions
GroupInterventionDescription
PatientsMagnetic Resonance ImagingPatients with verified singe large-scale mtDNA deletions and chronic progressive external ophthalmoplegia.
ControlsMagnetic Resonance ImagingHealthy controls matched for age and gender.
Patient group as ControlsMagnetic Resonance ImagingPatients with mitochondrial DNA 3243A\>G mutations
Primary Outcome Measures
NameTimeMethod
Fat fraction in the muscles of the lower bag, thighs and calves1 day

The investigators will make a 3-point Dixon scan of the muscles of the lower bag, thighs and calves and measure the fraction of fat in these muscles once per patient or control.

Secondary Outcome Measures
NameTimeMethod
Isokinetic muscle dynamometry of ankle flexion1 day

Isokinetic muscle dynamometry of ankle flexion. This is made on a Biodex 3 and done once per patient or control the same day as the MRI-scan is done. These results are correlated with the amount of non-fat-infiltrated muscle on the MRI scans.

Isokinetic muscle dynamometry of knee flexion.1 day

Isokinetic muscle dynamometry of knee flexion. This is made on a Biodex 3 and done once per patient or control the same day as the MRI-scan is done. These results are correlated with the amount of non-fat-infiltrated muscle on the MRI scans.

Isokinetic muscle dynamometry of ankle extension1 day

Isokinetic muscle dynamometry of ankle extension. This is made on a Biodex 3 and done once per patient or control the same day as the MRI-scan is done. These results are correlated with the amount of non-fat-infiltrated muscle on the MRI scans.

Isokinetic muscle dynamometry of knee extension1 day

Isokinetic muscle dynamometry of knee extension. This is made on a Biodex 3 and done once per patient or control the same day as the MRI-scan is done. These results are correlated with the amount of non-fat-infiltrated muscle on the MRI scans.

Trial Locations

Locations (1)

Neuromuscular Research Unit

🇩🇰

Copenhagen, Denmark

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