MedPath

Long-Term Follow-Up of a Cohort of Participants Prescribed Epidyolex in France in a Real-life Setting

Active, not recruiting
Conditions
Seizures
Interventions
Registration Number
NCT05772429
Lead Sponsor
Jazz Pharmaceuticals
Brief Summary

This is a multi-center, non-interventional and prospective study of patients receiving Epidyolex as part of standard clinical practice in France. The study will state an overview of patient characteristics and clinical history (including age, sex, diagnosis, duration of epilepsy, predominant seizure type, previous medications, current co-medications and Epidyolex dose), and an evaluation of retention rates, safety profile, seizure activity, changes in executive function and quality of life measured in a 2-year follow-up period.

Detailed Description

Not available

Recruitment & Eligibility

Status
ACTIVE_NOT_RECRUITING
Sex
All
Target Recruitment
158
Inclusion Criteria
  • Individuals for whom treatment with Epidyolex has been initiated by a physician with experience in the treatment of epilepsy.
  • The participant and/or parent(s)/legal representative is willing and able to give informed consent/assent for participation in the study.

Key

Exclusion Criteria
  • Previously initiated with Epidyolex before the start of the study (especially during the French early access program (EAP)).

Study & Design

Study Type
OBSERVATIONAL
Study Design
Not specified
Arm && Interventions
GroupInterventionDescription
EpidyolexEpidiolexParticipants will receive Epidyolex in accordance with their routine clinical practice as prescribed by their physician.
Primary Outcome Measures
NameTimeMethod
Retention Rate Percentage After Initiation of Treatment With EpidyolexUp to 24 months post-dose.

Retention rate will be measured through assessing the frequency of seizures and the length of time on treatment before a seizure event.

Secondary Outcome Measures
NameTimeMethod
Percent Change From Baseline in Seizure Frequency (Average Per 28 Days)Up to 24 months post-dose.
Change From Baseline in Behavior Rating Inventory of Executive Function, Adult Version (BRIEF- A) Score in Participants Aged >18 YearsBaseline; Up to 24 months post-dose.

BRIEF-A is a patient-reported scale to measure various aspects of adult executive functioning and self-regulation in the person's everyday environment. It is a 75-item questionnaire that participants rate on a 3-point Likert scale (1 = behavior is never observed to 3 = behavior is often observed). Higher scores indicate greater impairment in executive functioning.

Maximum Dose of Epidyolex Administered to ParticipantsUp to 24 months post-dose.
Change From Baseline in Behavior Rating Inventory of Executive Function (BRIEF) Score in Participants Aged 6 to 18 YearsBaseline; Up to 24 months post-dose.

BRIEF is an 86-item questionnaire used to assess the executive function behaviors at home and at school for children and adolescents ages 5-18. High scores obtained on the BRIEF suggest a higher level of dysfunction in a specific domain of executive functions. The BRIEF rating scores is an ordinal set of a technically summarized degree of disorder in functionality: Never = 1 (Minimum), Sometimes = 2 and Often = 3 (Maximum).

100% Responder (Seizure Freedom) RateUp to 24 months post-dose.
Number of Seizure-Free Days (Average Per 28 Days)Up to 24 months post-dose.
Longest Duration of Seizure-Free Days in the Last 28 DaysUp to 24 months post-dose.
Change From Baseline in Behavior Rating Inventory of Executive Function, Preschool Version (BRIEF-P) Score in Participants Aged ≤5 YearsBaseline; Up to 24 months post-dose.

The BRIEF-P is a 63-item questionnaire which consists of a single Rating Form used by parents, teachers, and day care providers to assess a child's executive functions within the context of their everyday environments--home and preschool. High scores obtained on the BRIEF-P suggest a higher level of dysfunction in a specific domain of executive functions. The BRIEF rating scores is an ordinal set of a technically summarized degree of disorder in functionality: Never = 1 (Minimum), Sometimes = 2 and Often = 3 (Maximum).

50% Responder RateUp to 24 months post-dose.
Modal Dose of Epidyolex Administered to ParticipantsUp to 24 months post-dose.
Change from Baseline in Average Daily Dosage of Concomitant Anti-Epileptic Drugs (AEDs) and Other MedicinesUp to 24 months post-dose.
Use of Rescue Medication Per MonthUp to 24 months post-dose.

A month is defined as 28 days.

Physician Global Clinical Impression of Change (PGIC) ScoreUp to 24 months post-dose.

The PGIC comprises the following question: "Please assess the change in the patient's general functional abilities since enrollment," scored on a seven-point scale from 1 (Very Much Improved) to 7 (Very Much Worse). Lower scores on the scale indicate a better quality of life.

75% Responder RateUp to 24 months post-dose.
Caregiver Global Impression of Change (CGIC) ScoreUp to 24 months post-dose.

The CGIC comprises of the following question: "Since your child started treatment, please assess the status of your child's overall condition (comparing their condition now to their condition before treatment)," scored on a seven-point scale from 1 (Very Much Improved) to 7 (Very Much Worse). Lower scores on the scale indicate a better quality of life.

Change from Baseline in Health Utility Index Mark II (HUI-2) ScoreUp to 24 months post-dose.

The HUI-2 is a generic measure of health status and health-related quality of life. There are 15 questions in the questionnaire with 1-week recall completed by the caregiver. Answers to the questionnaire are mapped into a classification system of 7 sets of utility scores (sensation, mobility, emotion, cognition, self-care, pain, and fertility) with a scoring scale of a minimum score of 0.00 (lack of functional capacity or most disabled) to a maximum of 1.00 (full function or no disability). A higher score indicates a better outcome.

Trial Locations

Locations (29)

APHP Pitié Salpetriere- service adulte

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Paris, France

APHP Robert Debré - service enfant

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Paris, France

APHP Necker - service enfant

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Paris, France

CHU Rennes - service adulte

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Rennes, France

CHU Amiens-service adulte

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Amiens, France

CHU Amiens-service enfant

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Amiens, France

CHU Angers - service adulte

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Angers, France

CHU Angers - service enfant

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Angers, France

CHU Bordeaux - service adulte

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Bordeaux, France

CHU Bordeaux,neuropédiatrie

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Bordeaux, France

GH Est - Hôpital Femme Mère Enfant

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Bron, France

HCL - Lyon - service adulte

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Bron, France

CHU Dijon - service neurophysiologie clinique

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Dijon, France

CHU Grenoble - service adulte

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Grenoble, France

CHU Grenoble - service enfant

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Grenoble, France

APHP Kremlin Bicetre - service enfant

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Le Kremlin-Bicêtre, France

APHM - Marseille - service adulte

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Marseille, France

CHU Lille - service enfant

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Lille, France

Hôpital Salengro - service adulte

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Lille, France

Hôpital de la Timone - service enfant

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Marseille, France

CHU Nancy - service adulte

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Nancy, France

CHU Nancy - service enfant

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Nancy, France

CHU Rennes - service enfant

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Rennes, France

CHU Strasbourg - service enfant

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Strasbourg, France

Hôpital de Hautepierre - service adulte

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Strasbourg, France

CHU Toulouse - service adulte

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Toulouse, France

CHU Toulouse - service enfant

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Toulouse, France

Hôpital Bretonneau - service adulte

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Tours, France

Hôpital Clocheville - service enfant

🇫🇷

Tours, France

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