MedPath

Cytoxan, Fludara, and Antithymocyte Globulin Conditioning Followed By Stem Cell Transplant in Treating Fanconi Anemia

Phase 1
Completed
Conditions
Fanconi Anemia
Interventions
Biological: Anti-Thymocyte Globulin
Procedure: Hematopoietic Stem Cell Transplantation
Registration Number
NCT00630253
Lead Sponsor
Masonic Cancer Center, University of Minnesota
Brief Summary

RATIONALE: Giving chemotherapy, such as cyclophosphamide and fludarabine, before a donor stem cell transplant helps to remove the patient's cells to allow for the transplant cells to take and grow. It also helps stop the patient's immune system from rejecting the donor's stem cells. When the healthy stem cells from a donor are infused into the patient, they may help the patient's bone marrow make stem cells, red blood cells, white blood cells, and platelets. Sometimes the transplanted cells can make an immune response against the body's normal cells. Giving antithymocyte globulin and removing the T cells from the donor cells before transplant and giving cyclosporine before and after transplant may stop this from happening.

PURPOSE: This phase I/II trial is studying the side effects of cyclophosphamide, fludarabine, and antithymocyte globulin followed by donor stem cell transplant and to see how well it works in treating patients with Fanconi anemia.

Detailed Description

OBJECTIVES:

Primary

* To determine the probability of engraftment in patients with Fanconi anemia treated with cyclophosphamide, fludarabine phosphate, and antithymocyte globulin followed by HLA-genotypically identical sibling donor hematopoietic stem cell transplantation that is T-cell depleted.

Secondary

* To evaluate the incidence of acute graft-versus-host disease (GVHD) and chronic GVHD in patients treated with this regimen.

* To evaluate the incidence of regimen-related toxicity in these patients.

* To evaluate the 1-year survival of patients treated with this regimen.

* To evaluate the incidence of late secondary malignancies (e.g., squamous cell carcinoma of the head and neck or cervix) in patients treated with this regimen.

OUTLINE:

* Preparative cytoreductive therapy: Patients receive cyclophosphamide IV over 2 hours on days -6 to -3 and fludarabine phosphate IV over 30 minutes and anti-thymocyte globulin IV over 4-6 hours on days -6 to -2.

* T-cell depleted donor hematopoietic stem cell transplantation: Patients undergo T-cell depleted donor bone marrow or umbilical cord blood stem cell transplantation on day 0. Patients also receive filgrastim (G-CSF) IV beginning on day 1 and continuing until blood counts recover.

* Graft-versus-host disease prophylaxis: Patients receive cyclosporine IV over 2 hours or orally every 8-12 hours beginning on day -3 and continuing until day 100, followed by a taper. Patients will receive Mycophenolate Mofetil (MMF) therapy beginning on day -3 through day +30 or for 7 days after engraftment, whichever day is later, if no acute GVHD. Engraftment is defined as 1st day of 3 consecutive days of absolute neutrophil count \[ANC\] \> 0.5 x 10\^9/L.

After completion of study therapy, patients are followed periodically.

Recruitment & Eligibility

Status
COMPLETED
Sex
All
Target Recruitment
31
Inclusion Criteria
  • Patients must be <60 years of age with a diagnosis of Fanconi Anemia (FA).

  • Patients must have an HLA-A, B, DRB1 identical sibling donor. Patients and donors will be typed for HLA-A and B using serological or molecular techniques and for DRB1 using high resolution molecular typing.

  • Patients with FA must have moderately severe aplastic anemia (AA), early myelodysplastic syndrome (MDS) with no excess blasts with or without chromosomal abnormalities.

    • In patients <18 years of age, moderately severe aplastic anemia is defined as having at least one of the following:

      • platelet count <40 x 10^9/L
      • absolute neutrophil count (ANC) <10 x 10^8/L
      • Hgb <9 g/dL
    • In patients 18-60 years of age, moderately severe aplastic anemia is defined as having at least one of the following:

      • platelet count <20 x 10^9/L
      • absolute neutrophil count ANC <5 x 10^8/L
      • Hgb <8 g/dL
    • Early myelodysplastic syndrome, with multilineage dysplasia with < 5% blasts, with or without chromosomal anomalies.

  • Adequate major organ function including:

    • Cardiac: ejection fraction >45%
    • Hepatic: no clinical evidence of hepatic failure (e.g. coagulopathy, ascites)
    • Karnofsky performance status >70% or Lansky >50%
  • Women of child bearing age must be using adequate birth control and have a negative pregnancy test.

Exclusion Criteria
  • Active bacterial infection within one week of hematopoietic cell transplant (HCT)
  • Active fungal infection at time of HCT.
  • Late MDS with greater than 5% blasts in bone marrow.
  • Acute myelogenous leukemia (AML) or history of AML
  • Malignant solid tumor (e.g. squamous cell carcinoma of the head/neck/cervix) within 2 years of HCT.
  • Pregnant or lactating female.

Study & Design

Study Type
INTERVENTIONAL
Study Design
SINGLE_GROUP
Arm && Interventions
GroupInterventionDescription
Marrow IsolexHematopoietic Stem Cell Transplantationbone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow ClinimaxAnti-Thymocyte Globulinbone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
UCBHematopoietic Stem Cell TransplantationNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
Marrow IsolexAnti-Thymocyte Globulinbone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow ClinimaxHematopoietic Stem Cell Transplantationbone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
UCBAnti-Thymocyte GlobulinNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
Marrow IsolexCyclophosphamidebone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow IsolexFludarabinebone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow IsolexFilgrastimbone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow IsolexCyclosporinebone marrow processed using Isolex 300i (for patients enrolled through April 2010)
Marrow IsolexMycophenolate Mofetilbone marrow processed using Isolex 300i (for patients enrolled through April 2010)
UCBCyclophosphamideNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
UCBFludarabineNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
UCBCyclosporineNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
UCBFilgrastimNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
UCBMycophenolate MofetilNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
Marrow ClinimaxCyclophosphamidebone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Marrow ClinimaxFludarabinebone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Marrow ClinimaxFilgrastimbone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Marrow ClinimaxCyclosporinebone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Marrow ClinimaxMycophenolate Mofetilbone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Marrow IsolexMethylprednisolonebone marrow processed using Isolex 300i (for patients enrolled through April 2010)
UCBMethylprednisoloneNo processing Notes: sibling donor UCB is used as the stem cell source and co-enroll for unlicensed UCB registry
Marrow ClinimaxMethylprednisolonebone marrow processed using CliniMACS (for patients enrolled beginning with the August 2010 protocol version)
Primary Outcome Measures
NameTimeMethod
Number of Participants Experiencing Graft FailureFrom Day 1 to event, assessed up to100 days

graft failure = absolute neutrophil count (ANC) \<5 x 10\^8/L and an acellular bone marrow aspirate/biopsy

Secondary Outcome Measures
NameTimeMethod
Number of Participants With Chronic Graft-Versus-Host Disease (GVHD)1 Year

Chronic Graft-Versus-Host Disease is a severe long-term complication created by infusion of donor cells into a foreign host.

Number of Participants With Acute Graft-Versus-Host Disease (GVHD)Day 42

Acute Graft-Versus-Host Disease is a severe short-term complication created by infusion of donor cells into a foreign host.

Number of Participants Experiencing Overall Survival1 Year

The percentage of people in a study or treatment group who are alive for a certain period of time after they were diagnosed with or treated for a disease, such as cancer. Also called survival rate.

Overall survival will be defined as time from enrollment to date of death or censored at the date of last documented contact for patients still alive.

Number of Participants With Transplant Related DeathsDay 100

In the field of transplantation, toxicity is high and all deaths without previous relapse or progression are usually considered as related to transplantation

Trial Locations

Locations (1)

Masonic Cancer Center, University of Minnesota

🇺🇸

Minneapolis, Minnesota, United States

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