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Denosumab for Glucocorticoid-treated Children With Rheumatic Disorders

Phase 1
Withdrawn
Conditions
Osteoporosis
Glucocorticoid-induced Osteoporosis
Juvenile Rheumatoid Arthritis
Dermatomyositis
Polyarthritis
Vasculitis
Systemic Lupus Erythematosis
Interventions
Registration Number
NCT02418273
Lead Sponsor
Indiana University
Brief Summary

The purpose of this study is to evaluate denosumab as a novel treatment for bone loss in children treated with glucocorticoids for rheumatic disorders. This is a pilot Phase 1/2, randomized open-label, 12-month clinical trial of denosumab to assess its effect on bone resorption markers and bone mineral density (BMD) in children with rheumatic disorders, age 4 to 16 years, recruited within 1 month of starting a chronic systemic glucocorticoid regimen. Primary outcomes include suppression of bone turnover markers and safety assessments. Secondary outcomes include changes in bone density as measured by dual energy X-ray absorptiometry (DXA) and peripheral quantitative computed tomography (pQCT) densitometry at the radius and tibia.

Detailed Description

The purpose of this study is to evaluate denosumab as a novel treatment for bone loss in children treated with glucocorticoids for rheumatic disorders. Children with rheumatic disorders are at risk for low bone density and fractures from the inflammatory effects of the underlying disease, and also from direct effects of glucocorticoids on bone. This is a pilot Phase 1/2, randomized open-label, 12-month clinical trial of denosumab to assess its effect on bone resorption markers and BMD in children with rheumatic disorders, age 4 to 16 years, recruited within 1 month of starting a chronic systemic glucocorticoid regimen. Two different sequential doses will be administered to the intervention group and evaluation for safety and efficacy will be conducted at study visits. Primary outcomes include suppression of bone turnover markers and safety assessments. Secondary outcomes include changes in bone density as measured by dual energy X-ray absorptiometry (DXA) and peripheral quantitative computed tomography (pQCT) densitometry at the radius and tibia.

Recruitment & Eligibility

Status
WITHDRAWN
Sex
All
Target Recruitment
Not specified
Inclusion Criteria
  1. Age 4 to 16 years of age.
  2. Diagnosis of one of the following by a rheumatologist using standard criteria: juvenile dermatomyositis, juvenile idiopathic arthritis, systemic arthritis, seronegative or seropositive polyarthritis, psoriatic arthritis, systemic lupus or systemic vasculitis.
  3. Within 1 month of initiating glucocorticoids ≥0.5 mg/kg prednisone equivalent daily, planned for ≥ 6 months.
  4. BMD by DXA with Z-score < 0.0 on screening at lumbar spine or total body less head (TBLH).
Exclusion Criteria
  1. Previous treatment with a bisphosphonate, or other osteoporosis medication.
  2. Metabolic bone disorders besides glucocorticoid-induced osteoporosis; other disorders treated with systemic glucocorticoids (inflammatory bowel disease, severe pulmonary disease, nephrotic syndrome, etc.).
  3. Intent to treat with a tumor necrosis factor inhibitor or Interleukin 6 receptor antagonist during the first 6 months.
  4. Glomerular filtration rate < 30ml/min [pediatric estimated glomerular filtration rate = 0.413*(height/serum creatinine)] 75
  5. Planned orthopedic or other major surgery during the course of the study (at the time of enrollment)
  6. Significant dental caries, or plans to undergo invasive oral procedures during the subsequent 12 months.
  7. Known allergy to latex (drug packaging includes a natural rubber stopper), fructose intolerance or other denosumab contraindication.
  8. 25-hydroxyvitamin D (25OHD) level < 32 ng/dl. Subjects with 25OHD <32 ng/ml may be given cholecalciferol and rescreened.
  9. Hypocalcemia at screening (total serum calcium < 8.5 mg/dl after correction for albumin level).
  10. Chronic ventilator dependence, or other conditions increasing risk of participation.
  11. Pregnancy, or refusal to use acceptable contraception or abstain during the protocol (post-pubertal female).

Study & Design

Study Type
INTERVENTIONAL
Study Design
PARALLEL
Arm && Interventions
GroupInterventionDescription
DenosumabdenosumabThese subjects will receive two sequential doses of denosumab
Primary Outcome Measures
NameTimeMethod
Changes in bone turnover marker (N-telopeptide (NTX) /creatinine ratio).2 weeks, 1 month, 2 month, 3 month after each dose day.
Secondary Outcome Measures
NameTimeMethod
The changes in bone specific alkaline phosphorusFrom baseline to 1 week, 1,3,6 months after each dose day
Changes of BMD spine Z-scores12 month
Changes of volumetric BMD on peripheral quantitative computed tomography12 month
Changes of polar strength-strain index at tibia12 month
Changes of polar strength-strain index at radius12 month
Changes in bone strength index for compression at tibia.12 month
Changes in bone strength index for compression at radius12 month
The relationships of Interleukin 6 to baseline NTX/creatinine ratiobaseline visit
The relationships of Interleukin 6 to baseline DXAbaseline visit
The relationships of Interleukin 6 to baseline pQCT variables.baseline visit
The relationships of receptor activator of nuclear factor-kappa B ligand (RANKL) to baseline NTX/creatinine ratiobaseline visit
The relationships of receptor activator of nuclear factor-kappa B ligand (RANKL) to baseline BMDbaseline visit
The relationships of receptor activator of nuclear factor-kappa B ligand (RANKL) to baseline volumetric BMDbaseline visit
Dose limiting toxicities (DLTs), including hypocalcemia3 days, 1 week, 2, week, month 3,4,5,6 after each dose; or any other visits.
The duration of suppression of the NTX/creatinine ratioup to six months after each dose day
Changes of BMD Total body less head (TBLH) Z-scores12 month

Trial Locations

Locations (1)

Indiana University School of Medicine

🇺🇸

Indianapolis, Indiana, United States

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