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The Clinical And Subclinical Effects on Arterial Stiffness of Bosentan in Patients With Systemic Sclerosis

Phase 4
Completed
Conditions
Scleroderma, Systemic
Interventions
Registration Number
NCT02480335
Lead Sponsor
University Medical Center Groningen
Brief Summary

The aim of the study is to investigate whether bosentan added to usual care improves arterial stiffness after 3 months as measured as the pulse wave velocity (PWV) of the medium and large arteries corrected for blood pressure changes in patients with systemic sclerosis (SSc) with digital ulcers (DU). Patients will be randomized into a group with usual care and bosentan (n=10) or usual care only (n=10). PWV will be assessed at baseline, 3 months and 12 months.

Detailed Description

Rationale: Digital ischemia is a major problem in patients with Raynaud's phenomenon (RP), especially in those with underlying connective tissue diseases such as systemic sclerosis (SSc). SSc is hallmarked by microvascular disease which can be assessed by nailfold capillary microscopy (NCM) to identify specific capillary patterns. However, it appears that vascular damage is not restricted to the capillaries, but may also extend to more upstream hand and forearm arteries. This may not only be reflected by clinically relevant structural abnormalities such as obliteration, but also by decreases in arterial function. The best characterised in RP is the occurrence of vasospasms after cold exposure. However, evidence points out that major stiffening of the arteries also occurs, potentially exaggerating digital ischemia and other vascular complications in SSc.

Objective: To investigate whether bosentan added to usual care improves arterial stiffness after 3 months as measured as the pulse wave velocity of the medium and large arteries corrected for blood pressure changes in patients with systemic sclerosis with digital ulcers.

Intervention:

Group 1: Usual care AND bosentan 62.5 mg twice daily, titrated to 125 mg twice daily after one month if tolerated (n=10) Group 2: Usual care only (n=10)

Nature and extent of the burden and risks associated with participation, benefit and group relatedness: Bosentan is a registered product in the Netherlands. In this study, it will be used within its indication and not in combination with other products for which it has not been registered. Therefore no additional unknown uncertainties and increased overall risk are applicable for the investigational product. In the usual care group, treatment will not differ from clinical practice. To minimize the risk of patients not receiving the most appropriate treatment in the control group, regular visits and lab assessments are planned. Patients are allowed to start with bosentan in the usual care group if indicated by the treating physician. The study will consist of one screening and three study visits. During the latter, patients clinical signs and symptoms will be assessed, vascular lab will be performed, blood will be drawn, and subjects be asked to fill in questionnaire, all of which will have a duration of no more than 2 hours per visits. In total 3 times 24cc of blood will be collected, preferably in combination will routine lab assessments. These measures render the risks acceptable and the burden minimal for the subjects participating in the study.

Recruitment & Eligibility

Status
COMPLETED
Sex
All
Target Recruitment
20
Inclusion Criteria
  • 18 years or older
  • Systemic sclerosis based on the 2013 American College of Rheumatology/European League Against Rheumatism criteria
  • Raynaud's phenomenon
  • A history of digital ulcer disease
  • Assessable Pulse Wave Velocity measurement at baseline
  • Written informed consent
Exclusion Criteria
  • Hypersensitivity to the active substance or to any of the excipients
  • Systolic blood pressure lower than 85 mmHg
  • Moderate to severe hepatic impairment, i.e., Child-Pugh class B or C
  • Baseline values of liver aminotransferases, i.e., aspartate aminotransferases and/or alanine aminotransferases, greater than 3 times the upper limit of normal
  • Concomitant use of cyclosporine A
  • Pregnancy
  • Women of child-bearing potential who are not using reliable methods of contraception
  • Significant peripheral vascular disease as the sole consequence of atherosclerotic disease due to conventional vascular risk factors and coagulopathy

Study & Design

Study Type
INTERVENTIONAL
Study Design
PARALLEL
Arm && Interventions
GroupInterventionDescription
Usual care and bosentanbosentanUsual care and also treatment with bosentan.
Primary Outcome Measures
NameTimeMethod
Mean of right and left carotid-femoral arterial (i.e. aortic) Pulse Wave Velocity (cfPWV)3 months

assessed with Sphygmocor

Secondary Outcome Measures
NameTimeMethod
Capillaroscopic Skin Ulcer Risk Index (CSURI)3 and 12 months

With nailfold capillary microscopy

Right carotid-brachial arterial PWV (cbPWV)3 and 12 months

assessed with Sphygmocor

Right carotid-radial arterial PWV (crPWV)3 and 12 months

assessed with Sphygmocor

Microangiopathy Evolution Score (MES)3 and 12 months

With nailfold capillary microscopy

Prognostic Index for Digital Lesions (PILD)3 and 12 months

With nailfold capillary microscopy

Local PWV of the right radial artery (rPWV)3 and 12 months

ultrasound assessment using a MyLabOne Vascular machine

Local PWV of the left radial artery (rPWV)3 and 12 months

an ultrasound assessment using a MyLabOne Vascular machine

Local PWV of the right brachial artery (bPWV)3 and 12 months

an ultrasound assessment using a MyLabOne Vascular machine

Skin Autofluorescence3 and 12 months

assessed with the AGE Reader

Serum levels of tissue inhibitors of metalloproteinases (TIMP)3 and 12 months

determined using in-house enzyme-linked immunosorbent assays

Blood pressure of the brachial artery3 and 12 months

systolic/diastolic in mmHg

Mean of right and left carotid-femoral arterial (i.e. aortic) Pulse Wave Velocity (cfPWV)12 months

assessed with Sphygmocor

Local PWV of the left brachial artery (bPWV)3 and 12 months

an ultrasound assessment using a MyLabOne Vascular machine

Mean widened capillaries of 8 fingers (dig 2-5)3 and 12 months

number per finger, assessed with nailfold capillary microscopy

Mean giant capillaries of 8 fingers (dig 2-5)3 and 12 months

number per finger, assessed with nailfold capillary microscopy

Modified Rodnan Skin Score (mRSS)3 and 12 months

17 body areas are examined by clinical palpation and scored based on examiner judgement of skin thickness on a 4-point ordinal scale.

Scleroderma Health Assessment Questionnaire (SHAQ)3 and 12 months

questionnaire

Left carotid-brachial arterial PWV (cbPWV)3 and 12 months

assessed with Sphygmocor

Left carotid-radial arterial PWV (crPWV)3 and 12 months

assessed with Sphygmocor

Mean loop width of 8 fingers (dig 2-5)3 and 12 months

mm per capillary per finger, assessed with nailfold capillary microscopy

Blood flow in the hands in region of interest (ROI) 1: distal of the proximal interphalangeal (PIP) joint of the 3 middle fingers3 and 12 months

Measured by Laser Doppler Perfusion Imaging

Blood flow in the hands in ROI 2: distal of the metacarpal joints and proximal of the PIP joint3 and 12 months

Measured by Laser Doppler Perfusion Imaging

Number of new digital ulcers3 and 12 months

Number

Time to healing of digital ulcers3 and 12 months

In days

Urine albumin/creatinine ratio (ACR)3 and 12 months

Measured in two separate morning samples of urine

Serum levels of matrix metalloproteinases 93 and 12 months

determined using in-house enzyme-linked immunosorbent assays (ELISAs)

Mean capillary density of 8 fingers (dig 2-5)3 and 12 months

number per mm per finger, assessed with nailfold capillary microscopy

Blood flow in the hands in ROI 3: the hand proximal of the metacarpal joints3 and 12 months

Measured by Laser Doppler Perfusion Imaging

Serum levels of matrix metalloproteinase 33 and 12 months

measured according to the manufacturer's instructions

Short Form (36)3 and 12 months

questionnaire

Plasma N-terminal of the prohormone brain natriuretic peptide (NT-proBNP)3 and 12 months

assessed using a routine assay

Trial Locations

Locations (1)

University Medical Center Groningen

🇳🇱

Groningen, Netherlands

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